Epistatic effect of APP717 mutation and apolipoprotein E genotype in familial Alzheimer's disease

Ann Neurol. 1995 Jul;38(1):124-7. doi: 10.1002/ana.410380120.

Abstract

We found a new familial Alzheimer's disease kindred in which the disease cosegregates with the APP717Val-->Ile mutation and in which all of the three most common apolipoprotein E (ApoE) alleles are represented. We studied the relationship between ApoE genotype and the clinical expression of the disease and found that in this amyloid precursor protein-mutated family, ApoE genotype influences the age at onset of the disease. Three mutated subjects heterozygous for the epsilon 4 allele had the earliest age at onset in this family, subjects heterozygous for the epsilon 2 allele had the latest age at onset, and subjects homozygous for the epsilon 3 allele had an intermediate age at onset. In this large kindred we also found an amyloid precursor protein-mutated subject 2.4 standard deviations older than the mean age at onset without clinical signs and symptoms of the disease and carrying the epsilon 2/epsilon 3 genotype.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Alzheimer Disease / genetics*
  • Amyloid beta-Protein Precursor / genetics*
  • Apolipoproteins E / genetics*
  • Base Sequence
  • Epistasis, Genetic*
  • Female
  • Genotype
  • Humans
  • Male
  • Middle Aged
  • Molecular Sequence Data
  • Mutation*
  • Pedigree

Substances

  • APP717
  • Amyloid beta-Protein Precursor
  • Apolipoproteins E

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