FIP1L1-PDGFRA fusion gene in T-lymphoblastic lymphoma: A case report

Cancer Rep (Hoboken). 2023 Jan;6(1):e1769. doi: 10.1002/cnr2.1769. Epub 2022 Dec 14.

Abstract

Background: T-lymphoblastic lymphoma (T-LBL) is an aggressive malignancy of T-lymphoid precursors, rarely co-occurring with myeloid/lymphoid neoplasms with eosinophilia (M/LNs-Eo), with consequent rearrangement of tyrosine kinase (TK)-related genes. The FIP1L1-PDGFRA fusion gene is the most frequent molecular abnormality seen in eosinophilia-associated myeloproliferative disorders, but is also present in acute myeloid leukemia (AML), T-lymphoblastic leukemia/lymphoma (TLL), or both simultaneously. T-LBL mainly affects children and young adults, involving lymph node, bone marrow, and thymus. It represents about 85% of all immature lymphoblastic lymphomas, whereas immature B-cell lymphomas comprise approximately 15% of all cases of LBL.

Case: In this case report, we present an example of T cell lymphoblastic lymphoma with coexistent eosinophelia, treated successfully with a tyrosine-kinase inhibitor (TKI).

Conclusion: FIP1L1-PDGFRA-positive T-LBL and myeloproliferative disorders have excellent response to low-dose treatment with (TKI) imatinib. Most patients achieve rapid and complete hematologic and molecular remission within weeks.

Keywords: FIP1L1-PDGFRA; T lymphoblastic lymphoma; TLL; eosinophilia.

Publication types

  • Case Reports

MeSH terms

  • Child
  • Eosinophilia* / diagnosis
  • Eosinophilia* / drug therapy
  • Eosinophilia* / genetics
  • Humans
  • Imatinib Mesylate / therapeutic use
  • Myeloproliferative Disorders* / complications
  • Myeloproliferative Disorders* / drug therapy
  • Myeloproliferative Disorders* / genetics
  • Oncogene Proteins, Fusion / genetics
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma* / diagnosis
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma* / drug therapy
  • Precursor Cell Lymphoblastic Leukemia-Lymphoma* / genetics
  • Precursor T-Cell Lymphoblastic Leukemia-Lymphoma* / diagnosis
  • Precursor T-Cell Lymphoblastic Leukemia-Lymphoma* / drug therapy
  • Precursor T-Cell Lymphoblastic Leukemia-Lymphoma* / genetics
  • Protein Kinase Inhibitors / therapeutic use
  • Receptor, Platelet-Derived Growth Factor alpha / genetics
  • Receptor, Platelet-Derived Growth Factor alpha / metabolism
  • Receptor, Platelet-Derived Growth Factor alpha / therapeutic use
  • mRNA Cleavage and Polyadenylation Factors / genetics
  • mRNA Cleavage and Polyadenylation Factors / therapeutic use

Substances

  • Receptor, Platelet-Derived Growth Factor alpha
  • Imatinib Mesylate
  • Protein Kinase Inhibitors
  • FIP1L1-PDGFRA fusion protein, human
  • Oncogene Proteins, Fusion
  • mRNA Cleavage and Polyadenylation Factors