Recombination of repeat elements generates somatic complexity in human genomes

Cell. 2022 Aug 4;185(16):3025-3040.e6. doi: 10.1016/j.cell.2022.06.032. Epub 2022 Jul 25.

Abstract

Non-allelic recombination between homologous repetitive elements contributes to evolution and human genetic disorders. Here, we combine short- and long-DNA read sequencing of repeat elements with a new bioinformatics pipeline to show that somatic recombination of Alu and L1 elements is widespread in the human genome. Our analysis uncovers tissue-specific non-allelic homologous recombination hallmarks; moreover, we find that centromeres and cancer-associated genes are enriched for retroelements that may act as recombination hotspots. We compare recombination profiles in human-induced pluripotent stem cells and differentiated neurons and find that the neuron-specific recombination of repeat elements accompanies chromatin changes during cell-fate determination. Finally, we report that somatic recombination profiles are altered in Parkinson's and Alzheimer's disease, suggesting a link between retroelement recombination and genomic instability in neurodegeneration. This work highlights a significant contribution of the somatic recombination of repeat elements to genomic diversity in health and disease.

Keywords: Alu; L1; NAHR; non-allelic homologous recombination; recombination; repeat elements; somatic mosaicism; structural variants.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alu Elements / genetics
  • Genome, Human*
  • Homologous Recombination
  • Humans
  • Long Interspersed Nucleotide Elements
  • Repetitive Sequences, Nucleic Acid
  • Retroelements*

Substances

  • Retroelements