Loss of synergistic transcriptional feedback loops drives diverse B-cell cancers

EBioMedicine. 2021 Sep:71:103559. doi: 10.1016/j.ebiom.2021.103559. Epub 2021 Aug 27.

Abstract

Background: The most common B-cell cancers, chronic lymphocytic leukemia/lymphoma (CLL), follicular and diffuse large B-cell (FL, DLBCL) lymphomas, have distinct clinical courses, yet overlapping "cell-of-origin". Dynamic changes to the epigenome are essential regulators of B-cell differentiation. Therefore, we reasoned that these distinct cancers may be driven by shared mechanisms of disruption in transcriptional circuitry.

Methods: We compared purified malignant B-cells from 52 patients with normal B-cell subsets (germinal center centrocytes and centroblasts, naïve and memory B-cells) from 36 donor tonsils using >325 high-resolution molecular profiling assays for histone modifications, open chromatin (ChIP-, FAIRE-seq), transcriptome (RNA-seq), transcription factor (TF) binding, and genome copy number (microarrays).

Findings: From the resulting data, we identified gains in active chromatin in enhancers/super-enhancers that likely promote unchecked B-cell receptor signaling, including one we validated near the immunoglobulin superfamily receptors FCMR and PIGR. More striking and pervasive was the profound loss of key B-cell identity TFs, tumor suppressors and their super-enhancers, including EBF1, OCT2(POU2F2), and RUNX3. Using a novel approach to identify transcriptional feedback, we showed that these core transcriptional circuitries are self-regulating. Their selective gain and loss form a complex, iterative, and interactive process that likely curbs B-cell maturation and spurs proliferation.

Interpretation: Our study is the first to map the transcriptional circuitry of the most common blood cancers. We demonstrate that a critical subset of B-cell TFs and their cognate enhancers form self-regulatory transcriptional feedback loops whose disruption is a shared mechanism underlying these diverse subtypes of B-cell lymphoma.

Funding: National Institute of Health, Siteman Cancer Center, Barnes-Jewish Hospital Foundation, Doris Duke Foundation.

Keywords: B-cell cancer; Epigenetics; Lymphoma; Super-enhancers; Transcriptional regulation and feedback.

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • B-Lymphocytes / immunology
  • B-Lymphocytes / metabolism*
  • Biomarkers
  • Cell Transformation, Neoplastic / genetics*
  • Cell Transformation, Neoplastic / metabolism
  • Chromatin Immunoprecipitation Sequencing
  • Computational Biology / methods
  • DNA Copy Number Variations
  • Enhancer Elements, Genetic
  • Epigenesis, Genetic
  • Female
  • Gene Expression Profiling
  • Gene Expression Regulation, Neoplastic*
  • Humans
  • Immunophenotyping
  • Leukemia, B-Cell / diagnosis
  • Leukemia, B-Cell / etiology*
  • Leukemia, B-Cell / metabolism
  • Lymphoma, B-Cell / diagnosis
  • Lymphoma, B-Cell / etiology*
  • Lymphoma, B-Cell / metabolism
  • Male
  • Middle Aged
  • Models, Biological
  • Oncogenes
  • Signal Transduction
  • Transcription Factors / metabolism
  • Transcription, Genetic*

Substances

  • Biomarkers
  • Transcription Factors