A mosaic PIK3CA variant in a young adult with diffuse gastric cancer: case report

Eur J Hum Genet. 2021 Sep;29(9):1354-1358. doi: 10.1038/s41431-021-00853-6. Epub 2021 Jun 1.

Abstract

Hereditary diffuse gastric cancer (HDGC) is associated with germline deleterious variants in CDH1 and CTNNA1. The majority of HDGC-suspected patients are still genetically unresolved, raising the need for identification of novel HDGC predisposing genes. Under the collaborative environment of the SOLVE-RD consortium, re-analysis of whole-exome sequencing data from unresolved gastric cancer cases (n = 83) identified a mosaic missense variant in PIK3CA in a 25-year-old female with diffuse gastric cancer (DGC) without familial history for cancer. The variant, c.3140A>G p.(His1047Arg), a known cancer-related somatic hotspot, was present at a low variant allele frequency (18%) in leukocyte-derived DNA. Somatic variants in PIK3CA are usually associated with overgrowth, a phenotype that was not observed in this patient. This report highlights mosaicism as a potential, and understudied, mechanism in the etiology of DGC.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Class I Phosphatidylinositol 3-Kinases / genetics*
  • Exome Sequencing
  • Female
  • Humans
  • Mosaicism*
  • Mutation, Missense
  • Stomach Neoplasms / genetics*
  • Stomach Neoplasms / pathology

Substances

  • Class I Phosphatidylinositol 3-Kinases
  • PIK3CA protein, human