Study of the collagen type VI alpha 3 (COL6A3) gene in Parkinson's disease

BMC Neurol. 2021 May 8;21(1):187. doi: 10.1186/s12883-021-02215-7.

Abstract

Background: To date, the genetic contribution to Parkinson's disease (PD) remains unclear. Mutations in the collagen type VI alpha 3 (COL6A3) gene were recently identified as a cause of isolated dystonia. Since PD and dystonia are closely related disorders with shared clinical and genetic characteristics, we explored the association between COL6A3 and PD in a Chinese cohort.

Methods: We performed genetic screening of COL6A3 in a Chinese cohort of 173 patients with sporadic PD and 200 healthy controls. We identified variants that are likely to have pathogenic effects based on: 1) a minor allele frequency of < 0.01; and 2) the variant being recognized as deleterious by at least 15 different in silico predicting tools. Finally, we tested the aggregate burden of COL6A3 on PD via SKAT-O analysis.

Results: First, we found compound heterozygous COL6A3 gene mutations in one early-onset PD patients. Then, we explored whether COL6A3 variants contributed to increased risk of developing PD in a Chinese population. We detected 21 rare non-synonymous variants. Pathogenicity predictions identified 7 novel non-synonymous variants as likely to be pathogenic. SKAT-O analysis further revealed that an aggregate burden of variants in COL6A3 contributes to PD (p = 0.038).

Conclusion: An increased aggregate burden of the COL6A3 gene was detected in patients with PD.

Keywords: COL6A3; Dystonia; Gene; Parkinson’s disease.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Asian People / genetics
  • Cohort Studies
  • Collagen Type VI / genetics*
  • Female
  • Genetic Testing
  • Humans
  • Male
  • Middle Aged
  • Mutation
  • Parkinson Disease / genetics*
  • Pedigree

Substances

  • COL6A3 protein, human
  • Collagen Type VI