UBTD1 regulates ceramide balance and endolysosomal positioning to coordinate EGFR signaling

Elife. 2021 Apr 22:10:e68348. doi: 10.7554/eLife.68348.

Abstract

To adapt in an ever-changing environment, cells must integrate physical and chemical signals and translate them into biological meaningful information through complex signaling pathways. By combining lipidomic and proteomic approaches with functional analysis, we have shown that ubiquitin domain-containing protein 1 (UBTD1) plays a crucial role in both the epidermal growth factor receptor (EGFR) self-phosphorylation and its lysosomal degradation. On the one hand, by modulating the cellular level of ceramides through N-acylsphingosine amidohydrolase 1 (ASAH1) ubiquitination, UBTD1 controls the ligand-independent phosphorylation of EGFR. On the other hand, UBTD1, via the ubiquitination of Sequestosome 1 (SQSTM1/p62) by RNF26 and endolysosome positioning, participates in the lysosomal degradation of EGFR. The coordination of these two ubiquitin-dependent processes contributes to the control of the duration of the EGFR signal. Moreover, we showed that UBTD1 depletion exacerbates EGFR signaling and induces cell proliferation emphasizing a hitherto unknown function of UBTD1 in EGFR-driven human cell proliferation.

Keywords: EGFR; UBTD1; cell biology; cell proliferation; ceramide; human; ubiquitination.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Acid Ceramidase / genetics
  • Acid Ceramidase / metabolism
  • Cell Line, Tumor
  • Cell Proliferation
  • Ceramides / metabolism*
  • ErbB Receptors / genetics
  • ErbB Receptors / metabolism
  • Gene Expression Regulation, Enzymologic
  • Gene Expression Regulation, Neoplastic
  • Humans
  • Kinetics
  • Lysosomes / enzymology*
  • Lysosomes / genetics
  • Male
  • Neoplasm Proteins / genetics
  • Neoplasm Proteins / metabolism
  • Phosphorylation
  • Prostatic Neoplasms / enzymology*
  • Prostatic Neoplasms / genetics
  • Prostatic Neoplasms / pathology
  • Proteolysis
  • Sequestosome-1 Protein / genetics
  • Sequestosome-1 Protein / metabolism
  • Signal Transduction
  • Ubiquitination
  • Ubiquitins / genetics
  • Ubiquitins / metabolism*

Substances

  • Ceramides
  • Neoplasm Proteins
  • RNF26 protein, human
  • SQSTM1 protein, human
  • Sequestosome-1 Protein
  • UBTD1 protein, human
  • Ubiquitins
  • EGFR protein, human
  • ErbB Receptors
  • ASAH1 protein, human
  • Acid Ceramidase

Grants and funding

The funders had no role in study design, data collection and interpretation, or the decision to submit the work for publication.