The underestimated burden of monogenic kidney disease in adults waitlisted for kidney transplantation

Genet Med. 2021 Jul;23(7):1219-1224. doi: 10.1038/s41436-021-01127-8. Epub 2021 Mar 12.

Abstract

Purpose: Chronic kidney disease (CKD) is a major health-care burden. Increasing evidence suggests that a considerable proportion of patients are affected by a monogenic kidney disorder.

Methods: In this study, the kidney transplantation waiting list at the Charité was screened for patients with undetermined cause of CKD. By next-generation sequencing (NGS) we targeted all 600 genes described and associated with kidney disease or allied disorders.

Results: In total, 635 patients were investigated. Of these, 245 individuals had a known cause of CKD (38.5%) of which 119 had a proven genetic disease (e.g., ADPKD, Alport). The other 340 patients (53.5%) were classified as undetermined diagnosis, of whom 87 had kidney failure (KF) onset <40 years. To this latter group genetic testing was offered as well as to those patients (n = 29) with focal segmental glomerulosclerosis (FSGS) and all individuals (n = 21) suspicious for thrombotic microangiopathy (TMA) in kidney biopsy. We detected diagnostic variants in 26 of 126 patients (20.6%) of which 14 of 126 (11.1%) were pathogenic or likely pathogenic. In another 12 of 126 (9.5%) patients, variants of unknown significance (VUS) were detected.

Conclusion: Our study demonstrates the diagnostic value of comprehensive genetic testing among patients with undetermined CKD.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Genetic Testing
  • Glomerulosclerosis, Focal Segmental* / epidemiology
  • Glomerulosclerosis, Focal Segmental* / genetics
  • Humans
  • Kidney
  • Kidney Transplantation*
  • Polycystic Kidney, Autosomal Dominant*
  • Renal Insufficiency, Chronic* / diagnosis
  • Renal Insufficiency, Chronic* / epidemiology
  • Renal Insufficiency, Chronic* / genetics