COCO/DAND5 inhibits developmental and pathological ocular angiogenesis

EMBO Mol Med. 2021 Mar 5;13(3):e12005. doi: 10.15252/emmm.202012005. Epub 2021 Feb 15.

Abstract

Neovascularization contributes to multiple visual disorders including age-related macular degeneration (AMD) and retinopathy of prematurity. Current therapies for treating ocular angiogenesis are centered on the inhibition of vascular endothelial growth factor (VEGF). While clinically effective, some AMD patients are refractory or develop resistance to anti-VEGF therapies and concerns of increased risks of developing geographic atrophy following long-term treatment have been raised. Identification of alternative pathways to inhibit pathological angiogenesis is thus important. We have identified a novel inhibitor of angiogenesis, COCO, a member of the Cerberus-related DAN protein family. We demonstrate that COCO inhibits sprouting, migration and cellular proliferation of cultured endothelial cells. Intravitreal injections of COCO inhibited retinal vascularization during development and in models of retinopathy of prematurity. COCO equally abrogated angiogenesis in models of choroidal neovascularization. Mechanistically, COCO inhibited TGFβ and BMP pathways and altered energy metabolism and redox balance of endothelial cells. Together, these data show that COCO is an inhibitor of retinal and choroidal angiogenesis, possibly representing a therapeutic option for the treatment of neovascular ocular diseases.

Keywords: COCO; angiogenesis; energy metabolism; ocular pathologies.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Choroidal Neovascularization* / drug therapy
  • Cocos*
  • Endothelial Cells
  • Humans
  • Intercellular Signaling Peptides and Proteins
  • Retina
  • Vascular Endothelial Growth Factor A

Substances

  • DAND5 protein, human
  • Intercellular Signaling Peptides and Proteins
  • Vascular Endothelial Growth Factor A

Associated data

  • GEO/GSE160099

Grants and funding