A Novel HGF/SF Receptor (MET) Agonist Transiently Delays the Disease Progression in an Amyotrophic Lateral Sclerosis Mouse Model by Promoting Neuronal Survival and Dampening the Immune Dysregulation

Int J Mol Sci. 2020 Nov 12;21(22):8542. doi: 10.3390/ijms21228542.

Abstract

Amyotrophic Lateral Sclerosis (ALS) is a fatal neurodegenerative disease with no effective treatment. The Hepatocyte Growth Factor/Scatter Factor (HGF/SF), through its receptor MET, is one of the most potent survival-promoting factors for motor neurons (MN) and is known as a modulator of immune cell function. We recently developed a novel recombinant MET agonist optimized for therapy, designated K1K1. K1K1 was ten times more potent than HGF/SF in preventing MN loss in an in vitro model of ALS. Treatments with K1K1 delayed the onset of muscular impairment and reduced MN loss and skeletal muscle denervation of superoxide dismutase 1 G93A (SOD1G93A) mice. This effect was associated with increased levels of phospho-extracellular signal-related kinase (pERK) in the spinal cord and sciatic nerves and the activation of non-myelinating Schwann cells. Moreover, reduced activated microglia and astroglia, lower T cells infiltration and increased interleukin 4 (IL4) levels were found in the lumbar spinal cord of K1K1 treated mice. K1K1 treatment also prevented the infiltration of T cells in skeletal muscle of SOD1G93A mice. All these protective effects were lost on long-term treatment suggesting a mechanism of drug tolerance. These data provide a rational justification for further exploring the long-term loss of K1K1 efficacy in the perspective of providing a potential treatment for ALS.

Keywords: HGF/SF; MET; SOD1G93A mice; T cells; amyotrophic lateral sclerosis; motor neurons; pERK.

MeSH terms

  • Amyotrophic Lateral Sclerosis / drug therapy
  • Amyotrophic Lateral Sclerosis / immunology
  • Amyotrophic Lateral Sclerosis / metabolism*
  • Animals
  • Astrocytes / cytology
  • Astrocytes / metabolism
  • Behavior, Animal
  • Cell Survival
  • Coculture Techniques
  • Disease Models, Animal
  • Disease Progression
  • Dogs
  • Extracellular Signal-Regulated MAP Kinases / metabolism
  • Gliosis / metabolism
  • Hepatocyte Growth Factor / agonists*
  • Humans
  • Immune System*
  • Interleukin-4 / metabolism
  • Kringles
  • Ligands
  • Madin Darby Canine Kidney Cells
  • Mice
  • Mice, Inbred C57BL
  • Mice, Transgenic
  • Microglia / metabolism
  • Motor Neurons / metabolism
  • Neurons / cytology*
  • Neurons / metabolism
  • Schwann Cells / metabolism
  • Spinal Cord / metabolism
  • T-Lymphocytes / cytology

Substances

  • HGF protein, human
  • HGF protein, mouse
  • Ligands
  • Interleukin-4
  • Hepatocyte Growth Factor
  • Extracellular Signal-Regulated MAP Kinases