Population genomic screening of all young adults in a health-care system: a cost-effectiveness analysis

Genet Med. 2019 Sep;21(9):1958-1968. doi: 10.1038/s41436-019-0457-6. Epub 2019 Feb 18.

Abstract

Purpose: To consider the impact and cost-effectiveness of offering preventive population genomic screening to all young adults in a single-payer health-care system.

Methods: We modeled screening of 2,688,192 individuals, all adults aged 18-25 years in Australia, for pathogenic variants in BRCA1/BRCA2/MLH1/MSH2 genes, and carrier screening for cystic fibrosis (CF), spinal muscular atrophy (SMA), and fragile X syndrome (FXS), at 71% testing uptake using per-test costs ranging from AUD$200 to $1200 (~USD$140 to $850). Investment costs included genetic counseling, surveillance, and interventions (reimbursed only) for at-risk individuals/couples. Cost-effectiveness was defined below AUD$50,000/DALY (disability-adjusted life year) prevented, using an incremental cost-effectiveness ratio (ICER), compared with current targeted testing. Outcomes were cancer incidence/mortality, disease cases, and treatment costs reduced.

Results: Population screening would reduce variant-attributable cancers by 28.8%, cancer deaths by 31.2%, and CF/SMA/FXS cases by 24.8%, compared with targeted testing. Assuming AUD$400 per test, investment required would be between 4 and 5 times higher than current expenditure. However, screening would lead to substantial savings in medical costs and DALYs prevented, at a highly cost-effective ICER of AUD$4038/DALY. At AUD$200 per test, screening would approach cost-saving for the health system (ICER = AUD$22/DALY).

Conclusion: Preventive genomic screening in early adulthood would be highly cost-effective in a single-payer health-care system, but ethical issues must be considered.

Keywords: cancer; cost-effectiveness analysis; population genomic screening; preconception carrier screening; prevention.

MeSH terms

  • Adolescent
  • Adult
  • Australia / epidemiology
  • BRCA1 Protein / genetics
  • BRCA2 Protein / genetics
  • Cost-Benefit Analysis / economics
  • Cystic Fibrosis / diagnosis*
  • Cystic Fibrosis / epidemiology
  • Cystic Fibrosis / genetics
  • Delivery of Health Care / economics
  • Female
  • Fragile X Syndrome / diagnosis*
  • Fragile X Syndrome / epidemiology
  • Fragile X Syndrome / genetics
  • Humans
  • Male
  • Metagenomics / economics
  • Muscular Atrophy, Spinal / diagnosis*
  • Muscular Atrophy, Spinal / epidemiology
  • Muscular Atrophy, Spinal / genetics
  • MutL Protein Homolog 1 / genetics
  • MutS Homolog 2 Protein / genetics
  • Neoplasms / diagnosis*
  • Neoplasms / epidemiology
  • Neoplasms / genetics
  • Quality-Adjusted Life Years
  • Young Adult

Substances

  • BRCA1 Protein
  • BRCA1 protein, human
  • BRCA2 Protein
  • MLH1 protein, human
  • MSH2 protein, human
  • MutL Protein Homolog 1
  • MutS Homolog 2 Protein