The miRNA biogenesis pathway prevents inappropriate expression of injury response genes in developing and adult Schwann cells

Glia. 2018 Dec;66(12):2632-2644. doi: 10.1002/glia.23516. Epub 2018 Oct 8.

Abstract

Proper function of the nervous system depends on myelination. In peripheral nerves, Schwann cells (SCs) myelinate axons and the miRNA biogenesis pathway is required for developmental myelination and myelin maintenance. However, regulatory roles of this pathway at different stages of myelination are only partially understood. We addressed the requirement of the core miRNA biogenesis pathway components Dgcr8, Drosha, and Dicer in developing and adult SCs using mouse mutants with a comparative genetics and transcriptomics approach. We found that the microprocessor components Dgcr8 and Drosha are crucial for axonal radial sorting and to establish correct SC numbers upon myelination. Transcriptome analyses revealed a requirement of the microprocessor to prevent aberrantly increased expression of injury-response genes. Those genes are predicted targets of abundant miRNAs in sciatic nerves (SNs) during developmental myelination. In agreement, Dgcr8 and Dicer are required for proper maintenance of the myelinated SC state, where abundant miRNAs in adult SNs are predicted to target injury-response genes. We conclude that the miRNA biogenesis pathway in SCs is crucial for preventing inappropriate activity of injury-response genes in developing and adult SCs.

Keywords: Schwann cells; development; injury; miRNAs; peripheral nervous system.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Animals, Newborn
  • Connexins / genetics
  • Connexins / metabolism
  • DEAD-box RNA Helicases / genetics
  • DEAD-box RNA Helicases / metabolism
  • Female
  • Gap Junction beta-1 Protein
  • Gene Expression Profiling
  • Gene Expression Regulation, Developmental / genetics
  • Gene Expression Regulation, Developmental / physiology*
  • Male
  • Mice
  • Mice, Inbred C57BL
  • Mice, Transgenic
  • MicroRNAs / genetics
  • MicroRNAs / metabolism*
  • Microscopy, Electron
  • Myelin Sheath / pathology
  • Myelin Sheath / ultrastructure
  • RNA-Binding Proteins / genetics
  • RNA-Binding Proteins / metabolism
  • Ribonuclease III / genetics
  • Ribonuclease III / metabolism
  • Schwann Cells / metabolism
  • Schwann Cells / pathology*
  • Schwann Cells / ultrastructure
  • Sciatic Neuropathy / pathology*
  • Sciatic Neuropathy / prevention & control*
  • Signal Transduction / physiology*
  • Transcription Factors / metabolism

Substances

  • Connexins
  • Dgcr8 protein, mouse
  • MicroRNAs
  • RNA-Binding Proteins
  • Transcription Factors
  • Dicer1 protein, mouse
  • Drosha protein, mouse
  • Ribonuclease III
  • DEAD-box RNA Helicases