Possible role of CYP2B6 genetic polymorphisms in ifosfamide-induced encephalopathy: report of three cases

Fundam Clin Pharmacol. 2018 Jun;32(3):337-342. doi: 10.1111/fcp.12345. Epub 2018 Jan 25.

Abstract

Ifosfamide (IFA) is a potent alkylating antitumoral agent, but its use is limited by neurological side effects. IFA is a racemic mixture of two enantiomeric forms, R-IFA and S-IFA with a stereoselective metabolism by CYP3A4 and CYP2B6, leading either to bioactive or to toxic pathways. In three consecutive cases of pediatric patients who exhibited IFA-induced encephalopathy (IIE), genotyping of clinically relevant single-nucleotide polymorphisms associated with decreased CYP3A4 and CYP2B6 activities was performed. Genetic investigations revealed the presence of CYP2B6 rs4803419 (C>T) in one patient while the two others carried the CYP2B6*6 allelic variant. All patients carried CYP3A4 wild-type genotype (CYP3A4*1/*1). Because CYP2B6-deficient alleles may be responsible for an increased conversion of S-IFA into neurotoxic metabolites, screening for CYP2B6 polymorphisms may help to avoid IIE and improve clinical outcomes.

Keywords: CYP2B6; encephalopathy; ifosfamide metabolism; methylene blue; pharmacogenetics.

Publication types

  • Case Reports

MeSH terms

  • Administration, Intravenous
  • Adolescent
  • Antineoplastic Agents, Alkylating / adverse effects*
  • Antineoplastic Agents, Alkylating / metabolism
  • Bone Neoplasms / drug therapy*
  • Brain Diseases / chemically induced*
  • Brain Diseases / diagnosis
  • Brain Diseases / drug therapy
  • Brain Diseases / genetics*
  • Child
  • Cytochrome P-450 CYP2B6 / genetics*
  • Cytochrome P-450 CYP2B6 / metabolism
  • Female
  • Genetic Predisposition to Disease
  • Humans
  • Ifosfamide / adverse effects*
  • Ifosfamide / metabolism
  • Male
  • Methylene Blue / administration & dosage
  • Neuroprotective Agents / administration & dosage
  • Osteosarcoma / drug therapy*
  • Pharmacogenetics
  • Pharmacogenomic Variants*
  • Phenotype
  • Polymorphism, Single Nucleotide*
  • Risk Factors
  • Treatment Outcome

Substances

  • Antineoplastic Agents, Alkylating
  • Neuroprotective Agents
  • CYP2B6 protein, human
  • Cytochrome P-450 CYP2B6
  • Methylene Blue
  • Ifosfamide