Detergent Insoluble Proteins and Inclusion Body-Like Structures Immunoreactive for PRKDC/DNA-PK/DNA-PKcs, FTL, NNT, and AIFM1 in the Amygdala of Cognitively Impaired Elderly Persons

J Neuropathol Exp Neurol. 2018 Jan 1;77(1):21-39. doi: 10.1093/jnen/nlx097.

Abstract

Misfolded protein in the amygdala is a neuropathologic feature of Alzheimer disease and many other neurodegenerative disorders. We examined extracts from human amygdala (snap-frozen at autopsy) to investigate whether novel and as yet uncharacterized misfolded proteins would be detectable. Polypeptides from the detergent-insoluble, urea-soluble protein fractions of amygdala were interrogated using liquid chromatography-electrospray ionization-tandem mass spectrometry. Among the detergent-insoluble proteins identified in amygdala of demented subjects but not controls were Tau, TDP-43, Aβ, α-synuclein, and ApoE. Additional detergent-insoluble proteins from demented subjects in the high-molecular weight portion of SDS gels included NNT, TNIK, PRKDC (DNA-PK, or DNA-PKcs), ferritin light chain (FTL), AIFM1, SYT11, STX1B, EAA1, COL25A1, M4K4, CLH1, SQSTM, SYNJ1, C3, and C4. In follow-up immunohistochemical experiments, NNT, TNIK, PRKDC, AIFM1, and FTL were observed in inclusion body-like structures in cognitively impaired subjects' amygdalae. Double-label immunofluorescence revealed that FTL and phospho-PRKDC immunoreactivity colocalized partially with TDP-43 and/or Tau inclusion bodies. Western blots showed high-molecular weight "smears", particularly for NNT and PRKDC. A preliminary genetic association study indicated that rare NNT, TNIK, and PRKDC gene variants had nominally significant association with Alzheimer-type dementia risk. In summary, novel detergent-insoluble proteins, with evidence of proteinaceous deposits, were found in amygdalae of elderly, cognitively impaired subjects.

Keywords: ADSP; GWAS; LC-MS; Lewy; Phosphorylation; Proteomics; Tauopathy.

MeSH terms

  • Aged
  • Aged, 80 and over
  • Alzheimer Disease / metabolism*
  • Alzheimer Disease / pathology
  • Amygdala / metabolism*
  • Amygdala / pathology
  • Apoferritins / metabolism
  • Apoptosis Inducing Factor / metabolism
  • Chromatography, Liquid
  • Cognitive Dysfunction / metabolism*
  • Cognitive Dysfunction / pathology
  • DNA-Activated Protein Kinase / metabolism
  • DNA-Binding Proteins / metabolism
  • Humans
  • Inclusion Bodies / metabolism*
  • Inclusion Bodies / pathology
  • Mitochondrial Proteins / metabolism
  • NADP Transhydrogenase, AB-Specific / metabolism
  • Nuclear Proteins / metabolism
  • Proteomics
  • Tandem Mass Spectrometry

Substances

  • AIFM1 protein, human
  • Apoptosis Inducing Factor
  • DNA-Binding Proteins
  • FTL protein, human
  • Mitochondrial Proteins
  • Nuclear Proteins
  • Apoferritins
  • NADP Transhydrogenase, AB-Specific
  • NNT protein, human
  • DNA-Activated Protein Kinase
  • PRKDC protein, human