Successful management of a hydropic fetus with severe anemia and thrombocytopenia caused by anti-CD36 antibody

Int J Hematol. 2018 Feb;107(2):251-256. doi: 10.1007/s12185-017-2310-5. Epub 2017 Aug 16.

Abstract

Cases of CD36 deficiency are not rare in Asian populations, foetal and neonatal alloimmune thrombocytopenia (FNAIT) caused by anti-CD36 isoantibodies appears more frequent than other HPA alloantibodies. However, little is known about the treatment of anti-CD36 mediated FNAIT in this region. A Chinese male foetus, whose mother had a history of multiple intrauterine foetal demise and/or hydrops, was diagnosed with severe FNAIT at 27 weeks of gestational age. Immunological analysis revealed total absence of CD36 on platelets and monocytes from mother, caused by a 329-330delAC mutation of the CD36 gene. Anti-CD36 and anti-HLA class I antibodies were detected in the maternal serum, whereas only anti-CD36 isoantibodies were detectable in the foetal blood sample. Serial intrauterine transfusions with red blood cells (RBC) and platelets from a CD36null donor were performed to improve the severe anaemia and thrombocytopenia. The baby (2250 g; Apgar scores 10) was delivered vaginally at 32 weeks of gestation with normal haemoglobin (186 g/L) but low platelet count (48 × 109/L). After 2 days the platelet count rose to 121 × 109/L. This report suggests that intrauterine transfusions with compatible RBC and CD36null platelets are useful in preventing the deleterious clinical effects of anti-CD36-mediated severe FNAIT.

Keywords: Anti-CD36 antibody; Foetal anaemia and hydrops; Foetal and neonatal alloimmune thrombocytopenia; Intrauterine transfusion.

Publication types

  • Case Reports

MeSH terms

  • Anemia / embryology*
  • Anemia / immunology
  • Anemia / therapy*
  • Antibodies*
  • Blood Transfusion, Intrauterine*
  • CD36 Antigens / deficiency*
  • CD36 Antigens / immunology*
  • Erythrocyte Transfusion*
  • Female
  • Fetal Diseases / immunology
  • Fetal Diseases / therapy*
  • Gestational Age
  • Humans
  • Hydrops Fetalis / immunology*
  • Hydrops Fetalis / therapy*
  • Infant, Newborn
  • Male
  • Platelet Transfusion*
  • Pregnancy
  • Severity of Illness Index
  • Thrombocytopenia, Neonatal Alloimmune / immunology*
  • Thrombocytopenia, Neonatal Alloimmune / prevention & control*
  • Thrombocytopenia, Neonatal Alloimmune / therapy

Substances

  • Antibodies
  • CD36 Antigens