Myopathic mtDNA Depletion Syndrome Due to Mutation in TK2 Gene

Pediatr Dev Pathol. 2017 Sep-Oct;20(5):416-420. doi: 10.1177/1093526616686439. Epub 2017 Jan 25.

Abstract

Whole-exome sequencing was used to identify the disease gene(s) in a Spanish girl with failure to thrive, muscle weakness, mild facial weakness, elevated creatine kinase, deficiency of mitochondrial complex III and depletion of mtDNA. With whole-exome sequencing data, it was possible to get the whole mtDNA sequencing and discard any pathogenic variant in this genome. The analysis of whole exome uncovered a homozygous pathogenic mutation in thymidine kinase 2 gene ( TK2; NM_004614.4:c.323 C>T, p.T108M). TK2 mutations have been identified mainly in patients with the myopathic form of mtDNA depletion syndromes. This patient presents an atypical TK2-related myopathic form of mtDNA depletion syndromes, because despite having a very low content of mtDNA (<20%), she presents a slower and less severe evolution of the disease. In conclusion, our data confirm the role of TK2 gene in mtDNA depletion syndromes and expanded the phenotypic spectrum.

Keywords: TK2; mitochondria; mitochondrial DNA; mtDNA depletion syndromes; myopathy; whole-exome sequencing.

Publication types

  • Case Reports

MeSH terms

  • Child
  • Exome Sequencing
  • Female
  • Genetic Markers
  • Homozygote
  • Humans
  • Mitochondrial Diseases / diagnosis
  • Mitochondrial Diseases / genetics*
  • Muscular Diseases / diagnosis
  • Muscular Diseases / genetics*
  • Mutation*
  • Thymidine Kinase / genetics*

Substances

  • Genetic Markers
  • thymidine kinase 2
  • Thymidine Kinase

Supplementary concepts

  • Mitochondrial DNA Depletion Syndrome, Myopathic Form