Clinical and Immunological Characteristics of Autoimmune Addison Disease: A Nationwide Swedish Multicenter Study

J Clin Endocrinol Metab. 2017 Feb 1;102(2):379-389. doi: 10.1210/jc.2016-2522.

Abstract

Context: Studies of the clinical and immunological features of autoimmune Addison disease (AAD) are needed to understand the disease burden and increased mortality.

Objective: To provide upgraded data on autoimmune comorbidities, replacement therapy, autoantibody profiles, and cardiovascular risk factors.

Design, setting, and participants: A cross-sectional, population-based study that included 660 AAD patients from the Swedish Addison Registry (2008-2014). When analyzing the cardiovascular risk factors, 3594 individuals from the population-based survey in Northern Sweden, MONICA (monitoring of trends and determinants of cardiovascular disease), served as controls.

Main outcome measures: The endpoints were the prevalence of autoimmune comorbidities and cardiovascular risk factors. Autoantibodies against 13 autoantigens were determined.

Results: The proportion of 21-hydroxylase autoantibody-positive patients was 83%, and 62% of patients had ≥1 associated autoimmune diseases, more frequently coexisting in females (P < 0.0001). AAD patients had a lower body mass index (P < 0.0001) and prevalence of hypertension (P = 0.027) compared with controls. Conventional hydrocortisone tablets were used by 89% of the patients, with a mean dose of 28.1 ± 8.5 mg/d. The mean hydrocortisone equivalent dose normalized to the body surface was 14.8 ± 4.4 mg/m2/d. A greater hydrocortisone equivalent dose was associated with a greater incidence of hypertension (P = 0.046).

Conclusions: Careful monitoring of AAD patients is warranted to detect associated autoimmune diseases. Contemporary Swedish AAD patients did not have an increased prevalence of overweight, hypertension, type 2 diabetes mellitus, or hyperlipidemia. However, high glucocorticoid replacement doses could be a risk factor for hypertension.

Publication types

  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Addison Disease / complications
  • Addison Disease / drug therapy
  • Addison Disease / epidemiology
  • Addison Disease / immunology*
  • Adolescent
  • Adult
  • Aged
  • Autoantibodies / blood
  • Autoimmune Diseases / epidemiology
  • Autoimmune Diseases / immunology
  • Cardiovascular Diseases / epidemiology
  • Cardiovascular Diseases / etiology
  • Child
  • Child, Preschool
  • Comorbidity
  • Cross-Sectional Studies
  • Drug Administration Schedule
  • Female
  • Hormone Replacement Therapy / methods
  • Humans
  • Hydrocortisone / administration & dosage
  • Hydrocortisone / therapeutic use
  • Infant
  • Infant, Newborn
  • Male
  • Middle Aged
  • Registries
  • Risk Factors
  • Sweden / epidemiology
  • Young Adult

Substances

  • Autoantibodies
  • Hydrocortisone