Comparison of Huntington's disease CAG Repeat Length Stability in Human Motor Cortex and Cingulate Gyrus

J Huntingtons Dis. 2016 Oct 1;5(3):297-301. doi: 10.3233/JHD-160203.

Abstract

Huntington's disease is caused by expansion of the CAG repeat in Huntingtin. This repeat has shown tissue-specific instability in mouse models and in a small number of post-mortem human samples. We used small-pool PCR to generate a modified instability index to quantify CAG instability within two brain regions from six human samples where cell loss has been associated with motor and mood symptoms: the motor cortex and cingulate gyrus. The expanded allele demonstrated instability in both regions, with minimal instability in the unexpanded allele. Region-specific differences were not observed, suggesting symptomatology may not be determined by repeat length instability.

Keywords: Huntington’s disease; small-pool PCR.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Analysis of Variance
  • Gyrus Cinguli / pathology*
  • Humans
  • Huntingtin Protein / genetics*
  • Huntington Disease / genetics*
  • Huntington Disease / pathology*
  • Motor Cortex / pathology*
  • Trinucleotide Repeat Expansion / genetics*

Substances

  • HTT protein, human
  • Huntingtin Protein