Outcomes after Unrelated Umbilical Cord Blood Transplantation for Children with Osteopetrosis

Biol Blood Marrow Transplant. 2016 Nov;22(11):1997-2002. doi: 10.1016/j.bbmt.2016.07.015. Epub 2016 Jul 25.

Abstract

Hematopoietic stem cell transplantation (HSCT) is the only curative treatment for most children with osteopetrosis (OP). Timing of HSCT is critical; therefore, umbilical cord blood transplantation (UCBT) is an attractive option. We analyzed outcomes after UCBT in 51 OP children. Median age at UCBT was 6 months. Seventy-seven percent of the cord blood grafts had 0 or 1 HLA disparity with the recipient. Conditioning regimen was myeloablative (mostly busulfan-based in 84% and treosulfan-based in 10%). Antithymocyte globulin was given to 90% of patients. Median number of total nucleated and CD34+ cells infused was 14 × 107/kg and 3.4 × 105/kg, respectively. Median follow-up for survivors was 74 months. Cumulative incidence (CI) of neutrophil recovery was 67% with a median time to recovery of 23 days; 33% of patients had graft failure, 81% of engrafted patients had full donor engraftment, and 19% had mixed donor chimerism. Day 100 CI of acute graft-versus-host disease (grades II to IV) was 31% and 6-year CI of chronic graft-versus-host disease was 21%. Mechanical ventilation was required in 28%, and veno-occlusive disease was diagnosed in 16% of cases. Six-year overall survival rate was 46%. Comparative studies with other alternative donors should be performed to evaluate whether UCBT remains a valid alternative for children with OP without an HLA-matched donor.

Keywords: Osteopetrosis; Stem cell transplantation; Umbilical cord blood transplantation.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Child
  • Child, Preschool
  • Cord Blood Stem Cell Transplantation / adverse effects
  • Cord Blood Stem Cell Transplantation / methods*
  • Cord Blood Stem Cell Transplantation / mortality
  • Female
  • Graft Survival
  • Graft vs Host Disease
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Neutrophils
  • Osteopetrosis / mortality
  • Osteopetrosis / therapy*
  • Recovery of Function
  • Survival Analysis
  • Transplantation Conditioning / methods
  • Treatment Outcome
  • Unrelated Donors*