Whole-genome Linkage Analysis and Sequence Analysis of Candidate Loci in Familial Breast Cancer

Anticancer Res. 2015 Jun;35(6):3155-65.

Abstract

Background: Known breast cancer-predisposing genes account for fewer than 25% of all familial breast cancer cases and further studies are required to find the remaining high- and moderate-risk genes. We set-out to couple linkage analysis using microsatellite marker data and sequence analysis of linked regions in 13 non-BRCA1/2 families in order to find novel susceptibility loci and high-penetrant genes.

Materials and methods: Genotyping with 540 fluorescently-labeled microsatellite markers located on the 23 chromosomes at 7.25 cM resolution was used for primary linkage analysis and an additional 40 markers were used for fine-mapping of loci with a logarithm of odds (LOD) or heterogeneity LOD (HLOD) score greater than one. Whole-exome sequencing data of 28 members from all 13 families were used for the bioinformatics sequence analysis on the linked regions of these families.

Results: Linkage analysis identified three loci on chromosome 18q as a putative region of interest (overall LOD=1, HLOD=1.2). Sequencing analysis of the three linked regions on 18q and mutation prediction algorithms did reveal three probable damaging variants.

Conclusion: Overall, our study identified three weakly linked loci on 18q and three probable damaging variants of interest in the 13 families with breast cancer.

Keywords: Familial breast cancer; linkage analysis; microsatellite markers; next generation sequencing; sequencing analysis.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • BRCA1 Protein / genetics
  • BRCA2 Protein / genetics
  • Breast Neoplasms / genetics*
  • Breast Neoplasms / pathology
  • Chromosomes, Human, Pair 18 / genetics*
  • Exome / genetics
  • Female
  • Genetic Association Studies
  • Genetic Linkage*
  • Genetic Predisposition to Disease*
  • Genome, Human
  • Genotype
  • High-Throughput Nucleotide Sequencing
  • Humans
  • Male
  • Microsatellite Repeats / genetics
  • Pedigree

Substances

  • BRCA1 Protein
  • BRCA2 Protein
  • BRCA2 protein, human