Combined comparative genomic hybridization and transcriptomic analyses of ovarian granulosa cell tumors point to novel candidate driver genes

BMC Cancer. 2015 Apr 10:15:251. doi: 10.1186/s12885-015-1283-0.

Abstract

Background: Ovarian granulosa cell tumors (GCTs) are the most frequent sex cord-stromal tumors. Several studies have shown that a somatic mutation leading to a C134W substitution in the transcription factor FOXL2 appears in more than 95% of adult-type GCTs. Its pervasive presence suggests that FOXL2 is the main cancer driver gene. However, other mutations and genomic changes might also contribute to tumor formation and/or progression.

Methods: We have performed a combined comparative genomic hybridization and transcriptomic analyses of 10 adult-type GCTs to obtain a picture of the genomic landscape of this cancer type and to identify new candidate co-driver genes.

Results: Our results, along with a review of previous molecular studies, show the existence of highly recurrent chromosomal imbalances (especially, trisomy 14 and monosomy 22) and preferential co-occurrences (i.e. trisomy 14/monosomy 22 and trisomy 7/monosomy 16q). In-depth analyses showed the presence of recurrently broken, amplified/duplicated or deleted genes. Many of these genes, such as AKT1, RUNX1 and LIMA1, are known to be involved in cancer and related processes. Further genomic explorations suggest that they are functionally related.

Conclusions: Our combined analysis identifies potential candidate genes, whose alterations might contribute to adult-type GCT formation/progression together with the recurrent FOXL2 somatic mutation.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Comparative Genomic Hybridization
  • Core Binding Factor Alpha 2 Subunit / biosynthesis
  • Core Binding Factor Alpha 2 Subunit / genetics
  • Cytoskeletal Proteins / biosynthesis
  • Cytoskeletal Proteins / genetics
  • DNA Copy Number Variations / genetics
  • Female
  • Forkhead Box Protein L2
  • Forkhead Transcription Factors / genetics*
  • Gene Expression Profiling*
  • Gene Expression Regulation, Neoplastic
  • Genetic Association Studies
  • Genomics
  • Granulosa Cell Tumor / genetics*
  • Granulosa Cell Tumor / pathology
  • Humans
  • Neoplasm Proteins / biosynthesis*
  • Neoplasm Proteins / genetics
  • Point Mutation
  • Proto-Oncogene Proteins c-akt / biosynthesis
  • Proto-Oncogene Proteins c-akt / genetics

Substances

  • Core Binding Factor Alpha 2 Subunit
  • Cytoskeletal Proteins
  • FOXL2 protein, human
  • Forkhead Box Protein L2
  • Forkhead Transcription Factors
  • LIMA1 protein, human
  • Neoplasm Proteins
  • RUNX1 protein, human
  • AKT1 protein, human
  • Proto-Oncogene Proteins c-akt

Supplementary concepts

  • Granulosa cell tumor of the ovary