Genetics and Prognostication in Splenic Marginal Zone Lymphoma: Revelations from Deep Sequencing

Clin Cancer Res. 2015 Sep 15;21(18):4174-4183. doi: 10.1158/1078-0432.CCR-14-2759. Epub 2015 Mar 16.

Abstract

Purpose: Mounting evidence supports the clinical significance of gene mutations and immunogenetic features in common mature B-cell malignancies.

Experimental design: We undertook a detailed characterization of the genetic background of splenic marginal zone lymphoma (SMZL), using targeted resequencing and explored potential clinical implications in a multinational cohort of 175 patients with SMZL.

Results: We identified recurrent mutations in TP53 (16%), KLF2 (12%), NOTCH2 (10%), TNFAIP3 (7%), MLL2 (11%), MYD88 (7%), and ARID1A (6%), all genes known to be targeted by somatic mutation in SMZL. KLF2 mutations were early, clonal events, enriched in patients with del(7q) and IGHV1-2*04 B-cell receptor immunoglobulins, and were associated with a short median time to first treatment (0.12 vs. 1.11 years; P = 0.01). In multivariate analysis, mutations in NOTCH2 [HR, 2.12; 95% confidence interval (CI), 1.02-4.4; P = 0.044] and 100% germline IGHV gene identity (HR, 2.19; 95% CI, 1.05-4.55; P = 0.036) were independent markers of short time to first treatment, whereas TP53 mutations were an independent marker of short overall survival (HR, 2.36; 95 % CI, 1.08-5.2; P = 0.03).

Conclusions: We identify key associations between gene mutations and clinical outcome, demonstrating for the first time that NOTCH2 and TP53 gene mutations are independent markers of reduced treatment-free and overall survival, respectively.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • Cohort Studies
  • DNA Mutational Analysis
  • DNA-Binding Proteins / genetics
  • Female
  • Genetic Markers
  • High-Throughput Nucleotide Sequencing
  • Humans
  • Intracellular Signaling Peptides and Proteins / genetics
  • Kruppel-Like Transcription Factors / genetics
  • Lymphoma, B-Cell, Marginal Zone / diagnosis*
  • Lymphoma, B-Cell, Marginal Zone / genetics*
  • Male
  • Middle Aged
  • Multivariate Analysis
  • Mutation*
  • Myeloid Differentiation Factor 88 / genetics
  • Neoplasm Proteins / genetics
  • Nuclear Proteins / genetics
  • Prognosis
  • Receptor, Notch2 / genetics
  • Risk Factors
  • Splenic Neoplasms / diagnosis*
  • Splenic Neoplasms / genetics*
  • Transcription Factors / genetics
  • Treatment Outcome
  • Tumor Necrosis Factor alpha-Induced Protein 3
  • Tumor Suppressor Protein p53 / genetics

Substances

  • ARID1A protein, human
  • DNA-Binding Proteins
  • Genetic Markers
  • Intracellular Signaling Peptides and Proteins
  • KLF2 protein, human
  • KMT2D protein, human
  • Kruppel-Like Transcription Factors
  • MYD88 protein, human
  • Myeloid Differentiation Factor 88
  • NOTCH2 protein, human
  • Neoplasm Proteins
  • Nuclear Proteins
  • Receptor, Notch2
  • TP53 protein, human
  • Transcription Factors
  • Tumor Suppressor Protein p53
  • TNFAIP3 protein, human
  • Tumor Necrosis Factor alpha-Induced Protein 3