Two transcription factors, Pou4f2 and Isl1, are sufficient to specify the retinal ganglion cell fate

Proc Natl Acad Sci U S A. 2015 Mar 31;112(13):E1559-68. doi: 10.1073/pnas.1421535112. Epub 2015 Mar 16.

Abstract

As with other retinal cell types, retinal ganglion cells (RGCs) arise from multipotent retinal progenitor cells (RPCs), and their formation is regulated by a hierarchical gene-regulatory network (GRN). Within this GRN, three transcription factors--atonal homolog 7 (Atoh7), POU domain, class 4, transcription factor 2 (Pou4f2), and insulin gene enhancer protein 1 (Isl1)--occupy key node positions at two different stages of RGC development. Atoh7 is upstream and is required for RPCs to gain competence for an RGC fate, whereas Pou4f2 and Isl1 are downstream and regulate RGC differentiation. However, the genetic and molecular basis for the specification of the RGC fate, a key step in RGC development, remains unclear. Here we report that ectopic expression of Pou4f2 and Isl1 in the Atoh7-null retina using a binary knockin-transgenic system is sufficient for the specification of the RGC fate. The RGCs thus formed are largely normal in gene expression, survive to postnatal stages, and are physiologically functional. Our results indicate that Pou4f2 and Isl1 compose a minimally sufficient regulatory core for the RGC fate. We further conclude that during development a core group of limited transcription factors, including Pou4f2 and Isl1, function downstream of Atoh7 to determine the RGC fate and initiate RGC differentiation.

Keywords: cell fate specification; gene regulation; neural development; retinal development; transcription factors.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alleles
  • Animals
  • Basic Helix-Loop-Helix Transcription Factors / genetics
  • Basic Helix-Loop-Helix Transcription Factors / metabolism
  • Cell Cycle
  • Cell Differentiation
  • Cell Lineage*
  • Central Nervous System / metabolism
  • Electrophysiology
  • Female
  • Gene Expression Regulation, Developmental*
  • Homeodomain Proteins / metabolism*
  • In Situ Hybridization
  • LIM-Homeodomain Proteins / metabolism*
  • Male
  • Mice
  • Mice, Inbred C57BL
  • Mice, Transgenic
  • Microscopy, Fluorescence
  • Nerve Tissue Proteins / genetics
  • Nerve Tissue Proteins / metabolism
  • Retina / embryology
  • Retina / metabolism
  • Retinal Ganglion Cells / metabolism*
  • Stem Cells / cytology
  • Transcription Factor Brn-3B / metabolism*
  • Transcription Factors / metabolism*

Substances

  • Atoh7 protein, mouse
  • Basic Helix-Loop-Helix Transcription Factors
  • Homeodomain Proteins
  • LIM-Homeodomain Proteins
  • Nerve Tissue Proteins
  • Pou4f2 protein, mouse
  • Transcription Factor Brn-3B
  • Transcription Factors
  • insulin gene enhancer binding protein Isl-1