Reduced α-synuclein levels in cerebrospinal fluid in Parkinson's disease are unrelated to clinical and imaging measures of disease severity

Eur J Neurol. 2014 Mar;21(3):388-94. doi: 10.1111/ene.12176. Epub 2013 Apr 30.

Abstract

Background and purpose: The cerebrospinal fluid (CSF) concentration of α-synuclein may reflect the aggregation of α-synuclein in brain tissue that neuropathologically characterizes Parkinson's disease (PD). Although most studies in large cohorts report reduced CSF α-synuclein levels in PD, the available data to date are not consistent due to variation in group sizes, pre-analytical confounding factors and assay characteristics. Furthermore, it remains unclear whether CSF α-synuclein concentrations correlate with measures of disease severity. Acknowledging the methodological issues that emerged from previous studies, we evaluated whether CSF α-synuclein levels differ between patients with PD and controls, and relate to disease duration or severity.

Methods: α-Synuclein levels were measured in CSF samples of 53 well-characterized patients with PD and 50 healthy controls employing a recently developed time-resolved Förster's resonance energy transfer assay. In addition, we studied the relationship of CSF α-synuclein levels with disease duration, clinical measures of disease severity and the striatal dopaminergic deficit as measured by dopamine transporter binding and single photon emission computed tomography.

Results: In patients with PD, we observed a decrease in mean CSF α-synuclein levels that was unrelated to disease duration or measures of disease severity. Using total protein normalized α-synuclein, a sensitivity and specificity of 70% and 74% could be reached for distinguishing between patients with PD and controls.

Conclusion: CSF α-synuclein levels are reduced in patients with PD compared with healthy controls. However, sensitivity and specificity indicate that α-synuclein will not suffice as a single biomarker. CSF α-synuclein levels do not correlate with measures of disease severity, including striatal dopaminergic deficit.

Keywords: DAT-SPECT; Parkinson's disease; biomarker; cerebrospinal fluid; α-synuclein.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Aged
  • Aged, 80 and over
  • Case-Control Studies
  • Corpus Striatum / diagnostic imaging
  • Dopamine Plasma Membrane Transport Proteins / metabolism
  • Female
  • Fluorescence Resonance Energy Transfer
  • Humans
  • Male
  • Mental Status Schedule
  • Middle Aged
  • Parkinson Disease / cerebrospinal fluid*
  • Parkinson Disease / diagnostic imaging*
  • ROC Curve
  • Retrospective Studies
  • Statistics, Nonparametric
  • Tomography, Emission-Computed, Single-Photon*
  • alpha-Synuclein / cerebrospinal fluid*

Substances

  • Dopamine Plasma Membrane Transport Proteins
  • alpha-Synuclein