Adult-onset vanishing white matter disease due to a novel EIF2B3 mutation

Arch Neurol. 2012 Jun;69(6):765-68. doi: 10.1001/archneurol.2011.1942.

Abstract

Objective: To report a novel mutation in the gene EIF2B3 responsible for a late-onset form of vanishing white matter disease.

Design: Case report.

Setting: University teaching hospital.

Patient: A 29-year-old pregnant woman with a history of premature ovarian failure and hemiplegic migraines presented with a 10-week history of progressive confusion and headaches. Magnetic resonance imaging of the brain revealed a diffuse leukoencephalopathy.

Results: Sequencing of the exons and intron boundaries of EIF2B3 uncovered 2 missense mutations: c.260C>T(p.Ala87Val) and c.272G>A(p.Arg91His). To our knowledge,the latter missense mutation has never been previously reported.

Conclusion: This is the second report of adult-onset vanishing white matter disease due to mutations in EIF2B3 and the first report of the c.272G>A (p.Arg91His) missense mutation.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Brain / pathology*
  • DNA Mutational Analysis
  • Eukaryotic Initiation Factor-2B / genetics*
  • Female
  • Humans
  • Leukoencephalopathies / genetics*
  • Leukoencephalopathies / pathology
  • Magnetic Resonance Imaging
  • Mutation / genetics*
  • Pregnancy

Substances

  • Eukaryotic Initiation Factor-2B