Multiple primary malignancies and subtle mucocutaneous lesions associated with a novel PTEN gene mutation in a patient with Cowden syndrome: case report

BMC Med Genet. 2011 Mar 15:12:38. doi: 10.1186/1471-2350-12-38.

Abstract

Background: Cowden syndrome (CS) is a cancer predisposition syndrome associated with increased risk of breast, thyroid, and endometrial cancers, and is characterized by development of benign mucocutaneous lesions.

Case presentation: Here we report on a 58-year-old woman with multiple primary malignancies and subtle mucocutaneous lesions such as small polyps and wart-like papulas. Over a period of 23 years, she developed various malignant neoplasms including thyroid, ovarian, stomach, and colon carcinomas, and a benign meningioma. Direct sequencing analysis of the PTEN gene revealed a novel germline mutation (c.438delT, p.Leu146X).

Conclusion: This case demonstrates that Cowden syndrome is a multi-system disease that can result in the development of multiple malignant and benign tumors.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Codon, Nonsense
  • Colonic Neoplasms / genetics
  • Fatal Outcome
  • Female
  • Frameshift Mutation
  • Germ-Line Mutation*
  • Hamartoma Syndrome, Multiple / genetics*
  • Hamartoma Syndrome, Multiple / pathology
  • Humans
  • Meningeal Neoplasms / genetics
  • Meningioma / genetics
  • Middle Aged
  • Neoplasms, Multiple Primary / genetics*
  • Ovarian Neoplasms / genetics
  • PTEN Phosphohydrolase / genetics*
  • Sequence Deletion
  • Stomach Neoplasms / genetics
  • Thyroid Neoplasms / genetics

Substances

  • Codon, Nonsense
  • PTEN Phosphohydrolase
  • PTEN protein, human