A truncating mutation in GPSM2 is associated with recessive non-syndromic hearing loss

Clin Genet. 2012 Mar;81(3):289-93. doi: 10.1111/j.1399-0004.2011.01654.x. Epub 2011 Mar 15.

Abstract

Hereditary deafness is a genetically heterogeneous phenotype for which more than 100 genomic loci have been identified thus far. By analysis of a consanguineous Palestinian family, GPSM2 was recently discovered to be the cause of autosomal recessive non-syndromic hearing loss DFNB82. Here, we report a second truncating mutation, GPSM2 p.Q562X, identified via autozygosity mapping in a consanguineous Turkish family. This report provides evidence for allelic heterogeneity of GPSM2 and confirms its causative role for non-syndromic deafness.

Publication types

  • Case Reports
  • Research Support, American Recovery and Reinvestment Act
  • Research Support, N.I.H., Extramural

MeSH terms

  • Consanguinity
  • Female
  • Genes, Recessive
  • Genotype
  • Hearing Loss / genetics*
  • Homozygote
  • Humans
  • Intracellular Signaling Peptides and Proteins / genetics*
  • Male
  • Mutation*
  • Polymorphism, Single Nucleotide
  • Turkey

Substances

  • GPSM2 protein, human
  • Intracellular Signaling Peptides and Proteins