Background: This is to describe a restricted sensory syndrome of unique distribution due to thalamic infarct.
Case description: We report a case of pure sensory disturbance involving the left intraoral and perioral regions and the tips of the thumb and forefinger of the left hand. Magnetic resonance imaging revealed a small infarct in the contralateral thalamus, presumably affecting the nucleus ventralis posterior.
Conclusions: This patient provides an excellent correlation between clinical findings and thalamic representation of body surface as established during stereotactic procedures.