Concomitant loss of dynorphin, NARP, and orexin in narcolepsy

Neurology. 2005 Oct 25;65(8):1184-8. doi: 10.1212/01.wnl.0000168173.71940.ab. Epub 2005 Sep 14.

Abstract

Background: Narcolepsy with cataplexy is associated with a loss of orexin/hypocretin. It is speculated that an autoimmune process kills the orexin-producing neurons, but these cells may survive yet fail to produce orexin.

Objective: To examine whether other markers of the orexin neurons are lost in narcolepsy with cataplexy.

Methods: We used immunohistochemistry and in situ hybridization to examine the expression of orexin, neuronal activity-regulated pentraxin (NARP), and prodynorphin in hypothalami from five control and two narcoleptic individuals.

Results: In the control hypothalami, at least 80% of the orexin-producing neurons also contained prodynorphin mRNA and NARP. In the patients with narcolepsy, the number of cells producing these markers was reduced to about 5 to 10% of normal.

Conclusions: Narcolepsy with cataplexy is likely caused by a loss of the orexin-producing neurons. In addition, loss of dynorphin and neuronal activity-regulated pentraxin may contribute to the symptoms of narcolepsy.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, U.S. Gov't, P.H.S.

MeSH terms

  • Aged
  • Autoantibodies / immunology
  • Autoimmune Diseases of the Nervous System / complications
  • Autoimmune Diseases of the Nervous System / pathology
  • Autoimmune Diseases of the Nervous System / physiopathology
  • Brain Mapping
  • C-Reactive Protein / deficiency
  • C-Reactive Protein / genetics
  • C-Reactive Protein / immunology
  • Dynorphins / deficiency
  • Dynorphins / genetics
  • Dynorphins / immunology
  • Humans
  • Hypothalamus / metabolism
  • Hypothalamus / pathology
  • Hypothalamus / physiopathology*
  • Immunohistochemistry
  • Intracellular Signaling Peptides and Proteins / deficiency*
  • Intracellular Signaling Peptides and Proteins / genetics
  • Intracellular Signaling Peptides and Proteins / immunology
  • Male
  • Middle Aged
  • Narcolepsy / etiology*
  • Narcolepsy / pathology
  • Narcolepsy / physiopathology*
  • Nerve Degeneration / genetics
  • Nerve Degeneration / pathology
  • Nerve Degeneration / physiopathology
  • Nerve Tissue Proteins / deficiency
  • Nerve Tissue Proteins / genetics
  • Nerve Tissue Proteins / immunology
  • Neural Pathways / metabolism
  • Neural Pathways / pathology
  • Neural Pathways / physiopathology
  • Neurodegenerative Diseases / complications*
  • Neurodegenerative Diseases / pathology
  • Neurodegenerative Diseases / physiopathology*
  • Neurons / metabolism
  • Neurons / pathology
  • Neuropeptides / deficiency*
  • Neuropeptides / genetics
  • Neuropeptides / immunology
  • Orexins
  • RNA, Messenger / metabolism

Substances

  • Autoantibodies
  • Intracellular Signaling Peptides and Proteins
  • Nerve Tissue Proteins
  • Neuropeptides
  • Orexins
  • RNA, Messenger
  • neuronal pentraxin
  • Dynorphins
  • C-Reactive Protein