Spondyloepiphyseal dysplasia tarda (SEDL, MIM #313400)

Eur J Hum Genet. 2003 Sep;11(9):639-42. doi: 10.1038/sj.ejhg.5201025.

Abstract

Spondyloepiphyseal dysplasia tarda (SEDL) is a radiologically distinct, X-chromosome linked primary skeletal dysplasia characterised by disproportionate short-trunked short stature, dysplasia of the large joints (hip) and flattened thoracic and lumber vertebral bodies. Molecular basis for SEDL has been elucidated by the identification of various mutations (currently >30) in the SEDL gene from Xp22 region. The function of the SEDL protein is not known although it is speculated that it may participate in the ER-to-Golgi transport as part of a novel highly conserved multiprotein TRAPP complex.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Carrier Proteins / genetics*
  • Chromosomes, Human, X / genetics*
  • Genetic Diseases, X-Linked / genetics*
  • Humans
  • Membrane Transport Proteins*
  • Mutation / genetics*
  • Osteochondrodysplasias / diagnosis
  • Osteochondrodysplasias / genetics*
  • Transcription Factors

Substances

  • Carrier Proteins
  • Membrane Transport Proteins
  • TRAPPC2 protein, human
  • Transcription Factors