Two novel point mutations of the XLRS1 gene in patients with X-linked juvenile retinoschisis

Am J Ophthalmol. 2002 Oct;134(4):622-4. doi: 10.1016/s0002-9394(02)01592-1.

Abstract

Purpose: To report two novel point mutations of the XLRS1 gene in two Japanese patients with X-linked juvenile retinoschisis.

Design: Observational case reports.

Methods: The exons, including the flanking introns of XLRS1, were amplified by polymerase chain reaction and analyzed by direct sequencing.

Results: One novel splice donor site mutation (IVS2 + 1g to a) and one missense mutation of exon 6 (Ala211Thr) were found.

Conclusions: Genetic findings identifying mutations in the XLRS1 gene will lead to earlier and more accurate diagnosis of X-linked juvenile retinoschisis.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Base Sequence / genetics
  • Child
  • Child, Preschool
  • Eye Proteins / genetics*
  • Humans
  • Male
  • Pedigree
  • Point Mutation*
  • Retinoschisis / genetics*
  • Retinoschisis / pathology

Substances

  • Eye Proteins
  • RS1 protein, human