Glutaric aciduria type I: pathomechanisms of neurodegeneration

J Inherit Metab Dis. 1999 Jun;22(4):392-403. doi: 10.1023/a:1005595921323.

Abstract

In organotypic corticostriatal and hippocampal slice cultures from rat brain, 3-hydroxyglutaric acid but not glutaric and glutaconic acids induced neurodegeneration by activation of NMDA receptors. Electrophysiological investigations (Xenopus laevis oocytes expressing glutamate receptors; rat mixed cortex culture) revealed no direct interaction of 3-hydroxyglutaric acid with glutamate receptors. We speculate that 3-hydroxyglutaric acid induces a mild energy deprivation that interferes with the voltage-dependent Mg(2+)-block of NMDA receptors.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Cerebral Cortex / drug effects
  • Cerebral Cortex / metabolism
  • Cerebral Cortex / pathology*
  • Culture Techniques
  • Glutarates / metabolism*
  • Glutarates / pharmacology
  • Glutarates / urine
  • Hippocampus / drug effects
  • Hippocampus / metabolism
  • Hippocampus / pathology*
  • Humans
  • Rats
  • Rats, Wistar
  • Receptors, N-Methyl-D-Aspartate / metabolism

Substances

  • 3-hydroxyglutaric acid
  • Glutarates
  • Receptors, N-Methyl-D-Aspartate
  • glutaric acid